Volume 18, Number 4Case ReviewCollateral Urethral Duplication in an Adult With Adult Polycystic Kidney DiseaseDunia Taufiq KhaledAmanda Feige SaltzmanLester Joesph PratsDuplications of the lower urinary tract are rare congenital anomalies that are usually accompanied by concomitant nonurologic anomalies; they are typically diagnosed in early childhood. In more rare cases these are isolated, leading to diagnosis later. We describe a 50-year-old man who remained asymptomatic and therefore undiagnosed for five decades. His is one of fewer than 20 cases in the literature describing urethral duplication in the coronal (collateral) plane, the more common variant being sagittal (dorsal-ventral) duplication. He is one of only four cases reported without concomitant midline anomaly. Furthermore, he is the sole case associated with adult polycystic kidney disease. [Rev Urol. 2016;18(4):242-245 doi: 10.3909/riu0705] © 2016 MedReviews®, LLCCollateral duplicationCoronal duplicationDuplicate urethraUrethral anomalyDuplication of lower urinary tract